The role of the electrocardiographic phenotype in risk stratification for sudden cardiac death in childhood hypertrophic cardiomyopathy


Por: Norrish G, Topriceanu C, Qu C, Field E, Walsh H, Ziólkowska L, Olivotto I, Passantino S, Favilli S, Anastasakis A, Vlagkouli V, Weintraub R, King I, Biagini E, Ragni L, Prendiville T, Duignan S, McLeod K, Ilina M, Fernández A, Bökenkamp R, Baban A, Drago F, Kubuš P, Daubeney PEF, Chivers S, Sarquella-Brugada G, César-Díaz S, Marrone C, Medrano C, Alvarez Garcia-Roves R, Uzun O, Gran F, Castro FJ, Gimeno JR, Barriales-Villa R, Rueda F, Adwani S, Searle J, Bharucha T, Siles A, Usano A, Rasmussen TB, Jones CB, Kubo T, Mogensen J, Reinhardt Z, Cervi E, Elliott PM, Omar RZ and Kaski JP

Publicada: 30 mar 2022 Ahead of Print: 1 mar 2021
Resumen:
Aims The 12-lead electrocardiogram (ECG) is routinely performed in children with hypertrophic cardiomyopathy (HCM). An ECG risk score has been suggested as a useful tool for risk stratification, but this has not been independently validated. This aim of this study was to describe the ECG phenotype of childhood HCM in a large, international, multi-centre cohort and investigate its role in risk prediction for arrhythmic events. Methods and results Data from 356 childhood HCM patients with a mean age of 10.1 years (+/- 4.5) were collected from a retrospective, multi-centre international cohort. Three hundred and forty-seven (97.5%) patients had ECG abnormalities at baseline, most commonly repolarization abnormalities (n = 277, 77.8%); left ventricular hypertrophy (n = 240, 67.7%); abnormal QRS axis (n = 126, 35.4%); or QT prolongation (n = 131, 36.8%). Over a median follow-up of 3.9 years (interquartile range 2.0-7.7), 25 (7%) had an arrhythmic event, with an overall annual event rate of 1.38 (95% CI 0.93-2.04). No ECG variables were associated with 5-year arrhythmic event on univariable or multivariable analysis. The ECG risk score threshold of >5 had modest discriminatory ability [C-index 0.60 (95% CI 0.484-0.715)], with corresponding negative and positive predictive values of 96.7% and 6.7% Conclusion In a large, international, multi-centre cohort of childhood HCM, ECG abnormalities were common and varied. No ECG characteristic, either in isolation or combined in the previously described ECG risk score, was associated with 5-year sudden cardiac death risk. This suggests that the role of baseline ECG phenotype in improving risk stratification in childhood HCM is limited.

Filiaciones:
Norrish G:
 Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK

 Institute of Cardiovascular Sciences, University College London, London, UK

Topriceanu C:
 Institute of Cardiovascular Sciences, University College London, London, UK

Qu C:
 Department of Statistical Science, University College London, London, UK

Field E:
 Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK

 Institute of Cardiovascular Sciences, University College London, London, UK

Walsh H:
 Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK

Ziólkowska L:
 Department of Cardiology, The Children's Memorial Health Institute, Warsaw, Poland

Olivotto I:
 Careggi University Hospital, Florence, Italy

Passantino S:
 Cardiology Unit, A Meyer Pediatric Hospital, Florence, Italy

Favilli S:
 Cardiology Unit, A Meyer Pediatric Hospital, Florence, Italy

Anastasakis A:
 Onassis Cardiac Surgery Center, Athens, Greece

Vlagkouli V:
 Onassis Cardiac Surgery Center, Athens, Greece

Weintraub R:
 The Royal Children's Hospital, Melbourne, Australia

 The Murdoch Children's Research Institute

 University of Melbourne, Australia

King I:
 The Murdoch Children's Research Institute

Biagini E:
 S. Orsola-Malpighi Hospital, Bologna, Italy

Ragni L:
 S. Orsola-Malpighi Hospital, Bologna, Italy

Prendiville T:
 Our Lady's Children's Hospital, Dublin, Ireland

Duignan S:
 Our Lady's Children's Hospital, Dublin, Ireland

McLeod K:
 Royal Hospital for Children, Glasgow, UK

Ilina M:
 Royal Hospital for Children, Glasgow, UK

Fernández A:
 Favaloro Foundation University Hospital, Buenos Aires, Argentina

Bökenkamp R:
 Leiden University Medical Center, Leiden, Netherlands

Baban A:
 Bambino Gesu Hospital, Rome, Italy

Drago F:
 Bambino Gesu Hospital, Rome, Italy

Kubuš P:
 University Hospital Motol, Prague, Czech Republic

Daubeney PEF:
 Royal Brompton and Harefield NHS Trust, London, UK

Chivers S:
 Royal Brompton and Harefield NHS Trust, London, UK

Sarquella-Brugada G:
 Arrhythmia and Inherited Cardiac Diseases Unit, Hospital Sant Joan de Déu, University of Barcelona, Spain

 Medical Sciences Department, School of Medicine, University of Girona

César-Díaz S:
 Arrhythmia and Inherited Cardiac Diseases Unit, Hospital Sant Joan de Déu, University of Barcelona, Spain

Marrone C:
 Papa Giovanni XXIII hospital, Bergamo, Italy

Medrano C:
 Hospital General Universitario Gregorio Marañón, Madrid, Spain

Alvarez Garcia-Roves R:
 Hospital General Universitario Gregorio Marañón, Madrid, Spain

Uzun O:
 University Hospital of Wales, Cardiff, UK

Gran F:
 Val d'Hebron University Hospital, Barcelona, Spain

Castro FJ:
 University Hospital Virgen de la Arrixaca, Murcia, Spain

Gimeno JR:
 University Hospital Virgen de la Arrixaca, Murcia, Spain

Barriales-Villa R:
 Complexo Hospitalario Universitario A Coruña, CIBERCV, A Coruña, Spain

Rueda F:
 Complexo Hospitalario Universitario A Coruña, CIBERCV, A Coruña, Spain

Adwani S:
 John Radcliffe Hospital, Oxford, UK

Searle J:
 John Radcliffe Hospital, Oxford, UK

Bharucha T:
 Southampton general Hospital, Southampton, UK

Siles A:
 Hospital Universitario Puerta de Hierro Majadahonda, CIBERCV, Madrid, Spain

 University Francisco de Vitoria, Pozuelo de Alarcon, Spain

Usano A:
 Hospital Universitario Puerta de Hierro Majadahonda, CIBERCV, Madrid, Spain

 University Francisco de Vitoria, Pozuelo de Alarcon, Spain

Rasmussen TB:
 Department of cardiology, Aarhus University Hospital, Aarhus, Denmark

Jones CB:
 Alder Hey Children's Hospital, Liverpool, UK

Kubo T:
 Department of Cardiology and Geriatrics, Kochi Medical School, Kochi University, Japan

Mogensen J:
 Odense University Hospital, Odense, Denmark

Reinhardt Z:
 The Freeman Hospital, Newcastle, UK

Cervi E:
 Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK

 Institute of Cardiovascular Sciences, University College London, London, UK

Elliott PM:
 Institute of Cardiovascular Sciences, University College London, London, UK

 St Bartholomew's Centre for Inherited Cardiovascular Diseases, St Bartholomew's Hospital, West Smithfield, London, UK

Omar RZ:
 Department of Statistical Science, University College London, London, UK

Kaski JP:
 Centre for Inherited Cardiovascular Diseases, Great Ormond Street Hospital, Great Ormond Street, London WC1N 3JH, UK

 Institute of Cardiovascular Sciences, University College London, London, UK
ISSN: 20474873





European Journal of Preventive Cardiology
Editorial
OXFORD UNIV PRESS, GREAT CLARENDON ST, OXFORD OX2 6DP, ENGLAND, Reino Unido
Tipo de documento: Article
Volumen: 29 Número: 4
Páginas: 645-653
WOS Id: 000755472600001
ID de PubMed: 33772274
imagen Green Submitted, hybrid

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