The alternative serotonin transporter promoter P2 impacts gene function in females with irritable bowel syndrome


Por: Mohr S, Fritz N, Hammer C, Martínez C, Berens S, Schmitteckert S, Wahl V, Schmidt M, Houghton LA, Goebel-Stengel M, Kabisch M, Götze D, Milovac I, D'Amato M, Zheng T, Röth R, Mönnikes H, Engel F, Gauss A, Tesarz J, Raithel M, Andresen V, Frieling T, Keller J, Pehl C, Stein-Thöringer C, Clarke G, Kennedy PJ, Cryan JF, Dinan TG, Quigley EMM, Spiller R, Beltrán C, Madrid AM, Torres V, Pérez de Arce E, Herzog W, Mayer EA, Sayuk G, Gazouli M, Karamanolis G, Kapur-Pojskic L, Bustamante M, Rabionet-Janssen R, Estivil X, Franke A, Lieb W, Boeckxstaens G, Wouters MM, Simrén M, Rappold GA, Vicario M, Santos J, Schaefert R, Lorenzo-Bermejo J and Niesler B

Publicada: 1 ago 2021 Ahead of Print: 1 jun 2021
Resumen:
Irritable bowel syndrome (IBS) is a gut-brain disorder in which symptoms are shaped by serotonin acting centrally and peripherally. The serotonin transporter gene SLC6A4 has been implicated in IBS pathophysiology, but the underlying genetic mechanisms remain unclear. We sequenced the alternative P2 promoter driving intestinal SLC6A4 expression and identified single nucleotide polymorphisms (SNPs) that were associated with IBS in a discovery sample. Identified SNPs built different haplotypes, and the tagging SNP rs2020938 seems to associate with constipation-predominant IBS (IBS-C) in females. rs2020938 validation was performed in 1978 additional IBS patients and 6,038 controls from eight countries. Meta-analysis on data from 2,175 IBS patients and 6,128 controls confirmed the association with female IBS-C. Expression analyses revealed that the P2 promoter drives SLC6A4 expression primarily in the small intestine. Gene reporter assays showed a functional impact of SNPs in the P2 region. In silico analysis of the polymorphic promoter indicated differential expression regulation. Further follow-up revealed that the major allele of the tagging SNP rs2020938 correlates with differential SLC6A4 expression in the jejunum and with stool consistency, indicating functional relevance. Our data consolidate rs2020938 as a functional SNP associated with IBS-C risk in females, underlining the relevance of SLC6A4 in IBS pathogenesis.

Filiaciones:
Mohr S:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

Fritz N:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

Hammer C:
 Department of Cancer Immunology, Genentech, South San Francisco, CA, USA

 Department of Human Genetics, Genentech, South San Francisco, CA, USA

Martínez C:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

 Institut de Recerca Biomèdica de Lleida (IRBLleida), Lleida, Spain

 Lleida Institute for Biomedical Research, Dr. Pifarré Foundation (IRBLleida), Lleida, Spain

Berens S:
 Department of General Internal Medicine and Psychosomatics, Heidelberg University Hospital, Heidelberg, Germany

Schmitteckert S:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

Wahl V:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

Schmidt M:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

 Department of Translational Brain Research, Central Institute of Mental Health

Houghton LA:
 St. James's University Hospital, University of Leeds, Leeds, UK

 Mayo Clinic, Jacksonville, FL, USA

Goebel-Stengel M:
 Department of Psychosomatic Medicine, University Hospital Tübingen, Tübingen, Germany

 Department of Internal Medicine and Gastroenterology, HELIOS Clinic Rottweil, Rottweil, Germany

Kabisch M:
 Institute of Medical Biometry and Informatics, Heidelberg University, Heidelberg, Germany

Götze D:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

Milovac I:
 Faculty of Medicine, University Banja Luka, Banja Luka, Bosnia and Herzegovina

D'Amato M:
 School of Biological Sciences, Monash University, Clayton, VIC, Australia

 Unit of Clinical Epidemiology, Department of Medicine Solna, Karolinska Institutet, Stockholm, Sweden

 Department of Gastrointestinal and Liver Diseases, Biodonostia HRI, San Sebastián, Spain

 Ikerbasque, Basque Foundation for Science, Bilbao, Spain

Zheng T:
 School of Biological Sciences, Monash University, Clayton, VIC, Australia

 Unit of Clinical Epidemiology, Department of Medicine Solna, Karolinska Institutet, Stockholm, Sweden

Röth R:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

 nCounter Core Facility, Department of Human Molecular Genetics, Heidelberg University Hospital, Heidelberg, Germany

Mönnikes H:
 Martin-Luther-Hospital, Berlin, Germany

Engel F:
 Department of General Internal Medicine and Psychosomatics, Heidelberg University Hospital, Heidelberg, Germany

Gauss A:
 Department of Gastroenterology, Infectious Diseases and Intoxications, Heidelberg University, Heidelberg, Germany

Tesarz J:
 Department of General Internal Medicine and Psychosomatics, Heidelberg University Hospital, Heidelberg, Germany

Raithel M:
 University of Erlangen, Erlangen, Germany

Andresen V:
 Israelitisches Krankenhaus, Hamburg, Germany

Frieling T:
 Helios Klinik Krefeld, Krefeld, Germany

Keller J:
 Israelitisches Krankenhaus, Hamburg, Germany

Pehl C:
 Krankenhaus Vilsbiburg, Vilsbiburg, Germany

Stein-Thöringer C:
 German Cancer Research Center, Heidelberg, Germany

Clarke G:
 Department of Psychiatry and Neurobehavioral Science, University College Cork, Cork, Ireland

 APC Microbiome Ireland, University College Cork, Cork, Ireland

Kennedy PJ:
 Department of Psychiatry and Neurobehavioral Science, University College Cork, Cork, Ireland

 APC Microbiome Ireland, University College Cork, Cork, Ireland

Cryan JF:
 Department of Psychiatry and Neurobehavioral Science, University College Cork, Cork, Ireland

 APC Microbiome Ireland, University College Cork, Cork, Ireland

 Department of Anatomy and Neuroscience, University College Cork, Cork, Ireland

Dinan TG:
 Department of Psychiatry and Neurobehavioral Science, University College Cork, Cork, Ireland

 APC Microbiome Ireland, University College Cork, Cork, Ireland

Quigley EMM:
 APC Microbiome Ireland, University College Cork, Cork, Ireland

 Lynda K. and David M. Underwood Center for Digestive Disorders, Houston Methodist Hospital, Weill Cornell Medical College, Houston, TX, USA

Spiller R:
 Nottingham Digestive Diseases Centre, University of Nottingham, Nottingham, UK

Beltrán C:
 Gastroenterology Unit, Hospital Clínico Universidad de Chile, Medicine Department, Universidad de Chile, Santiago de Chile, Chile

Madrid AM:
 Gastroenterology Unit, Hospital Clínico Universidad de Chile, Medicine Department, Universidad de Chile, Santiago de Chile, Chile

Torres V:
 Gastroenterology Unit, Hospital Clínico Universidad de Chile, Medicine Department, Universidad de Chile, Santiago de Chile, Chile

Pérez de Arce E:
 Gastroenterology Unit, Hospital Clínico Universidad de Chile, Medicine Department, Universidad de Chile, Santiago de Chile, Chile

Herzog W:
 Department of General Internal Medicine and Psychosomatics, Heidelberg University Hospital, Heidelberg, Germany

Mayer EA:
 Oppenheimer Center for Neurobiology of Stress, University of California, Los Angeles, CA, USA

Sayuk G:
 Washington University School of Medicine, St. Louis, MO, USA

Gazouli M:
 Laboratory of Biology, Medical School, National and Kapodistrian University of Athens, Athens, Greece

Karamanolis G:
 Academic Department of Gastroenterology, Medical School, National and Kapodistrian University of Athens, "Laikon" General Hospital, Athens, Greece

Kapur-Pojskic L:
 Institute for Genetic Engineering and Biotechnology, University of Sarajevo, Sarajevo, Bosnia and Herzegovina

Bustamante M:
 CRG, Centre for Genomic Regulation, Barcelona, Spain

 ISGlobal, Barcelona, Spain

Rabionet-Janssen R:
 Department of Genetics, Microbiology and Statistics, Faculty of Biology, IBUB, CIBERER, IRSJD, Universitat de Barcelona, Barcelona, Spain

Estivil X:
 CRG, Centre for Genomic Regulation, Barcelona, Spain

Franke A:
 Institute of Clinical Molecular Biology, Kiel, Germany

Lieb W:
 Institute of Epidemiology, Kiel, Germany

Boeckxstaens G:
 TARGID, University Hospital Leuven, Leuven, Belgium

Wouters MM:
 TARGID, University Hospital Leuven, Leuven, Belgium

Simrén M:
 Institute of Medicine, University of Gothenburg, Gothenburg, Sweden

Rappold GA:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

 Interdisciplinary Center for Neurosciences (IZN), Heidelberg University, Heidelberg, Germany

Vicario M:
 Institut de Recerca Vall d'Hebron, Hospital Vall d'Hebron, Barcelona, Spain

Santos J:
 Institut de Recerca Vall d'Hebron, Hospital Vall d'Hebron, Barcelona, Spain

Schaefert R:
 Department of Psychosomatic Medicine, Division of Internal Medicine, University Hospital Basel, Basel, Switzerland

 Faculty of Medicine, University of Basel, Basel, Switzerland

Lorenzo-Bermejo J:
 Institute of Medical Biometry and Informatics, Heidelberg University, Heidelberg, Germany

Niesler B:
 Department of Human Molecular Genetics, Institute of Human Genetics, Heidelberg University Hospital, Heidelberg, Germany

 nCounter Core Facility, Department of Human Molecular Genetics, Heidelberg University Hospital, Heidelberg, Germany

 Interdisciplinary Center for Neurosciences (IZN), Heidelberg University, Heidelberg, Germany
ISSN: 15821838





JOURNAL OF CELLULAR AND MOLECULAR MEDICINE
Editorial
WILEY, 111 RIVER ST, HOBOKEN 07030-5774, NJ, Reino Unido
Tipo de documento: Article
Volumen: 25 Número: 16
Páginas: 8047-8061
WOS Id: 000664873400001
ID de PubMed: 34165249
imagen Green Published, gold

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