Neurological Symptom Improvement After Re-Irradiation in Patients With Diffuse Intrinsic Pontine Glioma: A Retrospective Analysis of the SIOP-E-HGG/DIPG Project


Por: Chavaz L, Janssens GO, Bolle S, Mandeville H, Ramos-Albiac M, Van Beek K, Benghiat H, Hoeben B, Morales-La Madrid A, Seidel C, Kortmann RD, Hargrave D, Gandola L, Pecori E, van Vuurden DG, Biassoni V, Massimino M, Kramm CM and von Bueren AO

Publicada: 22 jun 2022 Ahead of Print: 22 jun 2022
Resumen:
PurposeThe aim of this study is to investigate the spectrum of neurological triad improvement in patients with diffuse intrinsic pontine glioma (DIPG) treated by re-irradiation (re-RT) at first progression. MethodsWe carried out a re-analysis of the SIOP-E retrospective DIPG cohort by investigating the clinical benefits after re-RT with a focus on the neurological triad (cranial nerve deficits, ataxia, and long tract signs). Patients were categorized as "responding" or "non-responding" to re-RT. To assess the interdependence between patients' characteristics and clinical benefits, we used a chi-square or Fisher's exact test. Survival according to clinical response to re-RT was calculated by the Kaplan-Meier method. ResultsAs earlier reported, 77% (n = 24/31) of patients had any clinical benefit after re-RT. Among 25/31 well-documented patients, 44% (n = 11/25) had improvement in cranial nerve palsies, 40% (n = 10/25) had improvement in long-tract signs, and 44% (11/25) had improvement in cerebellar signs. Clinical benefits were observed in at least 1, 2, or 3 out of 3 symptoms of the DIPG triad, in 64%, 40%, and 24%, respectively. Patients irradiated with a dose >= 20 Gy versus <20 Gy may improve slightly better with regard to ataxia (67% versus 23%; p-value = 0.028). The survival from the start of re-RT to death was not different between responding and non-responding DIPG patients (p-value = 0.871). ConclusionA median re-irradiation dose of 20 Gy provides a neurological benefit in two-thirds of patients with an improvement of at least one symptom of the triad. DIPG patients receiving >= 20 Gy appear to improve slightly better with regard to ataxia; however, we need more data to determine whether dose escalation up to 30 Gy provides additional benefits.

Filiaciones:
Chavaz L:
 Department of Pediatrics, Gynecology and Obstetrics, Division of Pediatric Hematology and Oncology, University Hospital of Geneva, Geneva, Switzerland

 Cansearch Research Platform for Pediatric Oncology and Hematology, Faculty of Medicine, Department of Pediatrics, Gynecology and Obstetrics, University of Geneva, Geneva, Switzerland

Janssens GO:
 Department of Radiation Oncology, University Medical Center Utrecht, Utrecht, Netherlands

 Princess Maxima Center for Pediatric Oncology, Utrecht, Netherlands

Bolle S:
 Department of Radiation Oncology, Gustave Roussy, Paris Saclay University, Villejuif, France

Mandeville H:
 Department of Radiotherapy, The Royal Marsden Hospital and Institute of Cancer Research, Sutton, United Kingdom

Ramos-Albiac M:
 Department of Radiation Oncology, Hospital Vall d'Hebron, Barcelona, Spain

Van Beek K:
 Department of Radiation Oncology, University Hospitals Leuven, Leuven, Belgium

Benghiat H:
 Department of Clinical Oncology, University Hospital Birmingham, Birmingham, United Kingdom

Hoeben B:
 Department of Radiation Oncology, University Medical Center Utrecht, Utrecht, Netherlands

 Princess Maxima Center for Pediatric Oncology, Utrecht, Netherlands

Morales-La Madrid A:
 Department of Pediatric Oncology, Hospital Sant Joan de Déu, Barcelona, Spain

Seidel C:
 Department of Radiation-Oncology, University Hospital Leipzig, Leipzig, Germany

Kortmann RD:
 Department of Radiation-Oncology, University Hospital Leipzig, Leipzig, Germany

Hargrave D:
 Pediatric Oncology Unit, Great Ormond Street Hospital for Children, London, United Kingdom

Gandola L:
 Pediatric Radiotherapy Unit, Fondazione Istituto di Ricovero e Cura a Carattere Scientifico (IRCCS) Istituto Nazionale dei Tumori, Milan, Italy

Pecori E:
 Pediatric Radiotherapy Unit, Fondazione Istituto di Ricovero e Cura a Carattere Scientifico (IRCCS) Istituto Nazionale dei Tumori, Milan, Italy

van Vuurden DG:
 Princess Maxima Center for Pediatric Oncology, Utrecht, Netherlands

 Department of Pediatric Oncology, Emma Children's Hospital, Amsterdam University Medical Centers (UMC), Vrije Universiteit Amsterdam, Amsterdam, Netherlands

Biassoni V:
 Pediatrics Unit, Fondazione Istituto di Ricovero e Cura a Carattere Scientifico (IRCCS) Istituto Nazionale dei Tumori, Milan, Italy

Massimino M:
 Pediatrics Unit, Fondazione Istituto di Ricovero e Cura a Carattere Scientifico (IRCCS) Istituto Nazionale dei Tumori, Milan, Italy

Kramm CM:
 Division of Pediatric Hematology and Oncology, University Medical Center Goettingen, Goettingen, Germany

von Bueren AO:
 Department of Pediatrics, Gynecology and Obstetrics, Division of Pediatric Hematology and Oncology, University Hospital of Geneva, Geneva, Switzerland

 Cansearch Research Platform for Pediatric Oncology and Hematology, Faculty of Medicine, Department of Pediatrics, Gynecology and Obstetrics, University of Geneva, Geneva, Switzerland
ISSN: 2234943X





Frontiers in Oncology
Editorial
FRONTIERS MEDIA SA, AVENUE DU TRIBUNAL FEDERAL 34, LAUSANNE CH-1015, SWITZERLAND, Suiza
Tipo de documento: Article
Volumen: 12 Número:
Páginas: 926196-926196
WOS Id: 000821310300001
ID de PubMed: 35814457
imagen Green Submitted, Green Accepted, gold

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