Clinical-Hematological Changes and Predictors of Severity in Acute Food Protein-Induced Enterocolitis Syndrome Reactions at Oral Food Challenge: A Multicenter Observational Study


Por: Argiz L, Valsami-Fokianos M, Arasi S, Barni S, Boscia S, Bracaglia G, Bracamonte T, Carballeira I, Dinardo G, Echeverria L, Garcia E, Garcia-Magan C, Gomez-Rial J, Gonzalez-Delgado P, Fiocchi A, Garriga T, Ibrahim T, Infante S, Machinena A, Mangone G, Mori F, Moure JD, O'Valle V, Pascal M, Pecora V, Prieto A, Quevedo S, Salas A, Vazquez-Cortes S, Vila L, Martinon-Torres F, Gomez-Carballa A, Boyle RJ and Vazquez-Ortiz M

Publicada: 1 sep 2024 Ahead of Print: 1 sep 2024
Resumen:
Background: Oral food challenge (OFC) is the criterion standard for diagnosis of acute food protein-induced enterocolitis syndrome (FPIES). No diagnostic/prognostic biomarkers are available, and OFC assessment criteria are not validated. Objective: To assess clinical-hematological changes and predictors of severity of FPIES reactions at OFC. Methods: This was an observational multicenter prospective study. Children aged 0 to 18 years diagnosed with acute FPIES were recruited at follow-up OFC in 12 tertiary centers in Spain and Italy. OFC outcomes (as positive/negative/inconclusive and mild/moderate/severe) were assessed on the basis of published "2017 FPIES Consensus" criteria. Clinical characteristics were recorded, and full blood cell count was done at baseline, reaction onset, and 4 hours later. Regression analysis was performed to assess predictors of severe reactions at OFC. Results: A total of 81 children had positive OFC (mild in 11% [9 of 81], moderate in 61% [49 of 81], and severe in 28% [23 of 81]). Increase in neutrophils and reduction in eosinophils, basophils, and lymphocytes were observed (P < .05). OFC was inconclusive in 19 cases despite objective signs or neutrophilia. Regression analysis showed that a 2-day OFC protocol where only 25% of an age-appropriate portion is given on day 1 (not sex, age, culprit food, cumulative dose, and previous reaction severity) was associated with reduced odds of severe reaction compared with giving multiple doses in a single day. Conclusions: Distinct hematological changes may help support FPIES diagnosis. Current OFC assessment criteria may not capture the broad spectrum of acute FPIES presentations. This 2-day protocol may be associated with a reduced risk of severe reactions. Future work should aim to develop safer OFC and non-OFC diagnostics for FPIES. (c) 2024 The Authors. Published by Elsevier Inc. on behalf of the American Academy of Allergy, Asthma & Immunology. This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/ licenses/by-nc-nd/4.0/). (J Allergy Clin Immunol Pract 2024;12:2454-67)

Filiaciones:
Argiz L:
 Department of Allergy, Clinica Universidad de Navarra, Pamplona, Spain

 RICORS Red De Enfermedades Inflamatorias (REI) - RD21/0002/0028, Madrid, Spain

Valsami-Fokianos M:
 National Heart and Lung Institute, Imperial College London, London, United Kingdom

Arasi S:
 Allergy Unit, Department of Pediatric Medicine, Bambino Gesù Children's Research Hospital, IRCCS, Rome, Italy

Barni S:
 Allergy Unit, Meyer Children's Hospital IRCCS, Florence, Italy

Boscia S:
 Division of Immunology, Meyer Children's Hospital IRCCS, Florence, Italy

 Department of Health Sciences, University of Florence, Florence, Italy

Bracaglia G:
 Laboratory Medicine, Bambino Gesù Children's Hospital IRCCS, Rome, Italy

Bracamonte T:
 Paediatric Allergy Section, Severo Ochoa University Hospital, Madrid, Spain

Carballeira I:
 Paediatric Allergy Section, Arquitecto Marcide Hospital, Coruña, Spain

Dinardo G:
 Department of Woman, Child and General and Specialized Surgery, University of Campania "Luigi Vanvitelli," Naples, Italy

Echeverria L:
 Paediatric Allergy Section, Severo Ochoa University Hospital, Madrid, Spain

Garcia E:
 Paediatric Allergy Section, Arquitecto Marcide Hospital, Coruña, Spain

Garcia-Magan C:
 Paediatrics Department, Hospital Clínico Universitario de Santiago de Compostela, Coruña, Spain

Gomez-Rial J:
 Genetics, Vaccines and Infections Research Group (GENVIP), Instituto de Investigación Sanitaria de Santiago (IDIS), University of Santiago de Compostela, Santiago de Compostela, Spain

Gonzalez-Delgado P:
 Allergy Department, General University Hospital, Alicante, Spain

Fiocchi A:
 Allergy Unit, Department of Pediatric Medicine, Bambino Gesù Children's Research Hospital, IRCCS, Rome, Italy

Garriga T:
 Paediatric Allergy Section, Vall D'Hebron University Hospital, Growth and Development Research Group, Vall d'Hebron Research Institute (VHIR), Barcelona, Spain

Ibrahim T:
 National Heart and Lung Institute, Imperial College London, London, United Kingdom

 Allergy and Immunology Division, Hamad Medical Corporation, Doha, Qatar

Infante S:
 Pediatric Allergy Unit, Hospital General Universitario Gregorio Marañón, Gregorio Marañón Health Research Institute, IiSGM, Madrid, Spain

Machinena A:
 Pediatric Allergy and Clinical Immunology Department, Hospital Sant Joan de Déu, Barcelona, Spain

Mangone G:
 Division of Immunology, Meyer Children's Hospital IRCCS, Florence, Italy

Mori F:
 Allergy Unit, Meyer Children's Hospital IRCCS, Florence, Italy

Moure JD:
 Paediatrics Department, Hospital Clínico Universitario de Santiago de Compostela, Coruña, Spain

O'Valle V:
 Paediatric Allergy Section, Severo Ochoa University Hospital, Madrid, Spain

Pascal M:
 Immunology Department, CDB, Hospital Clínic de Barcelona, Barcelona, Spain

 IDIBAPS, Universitat de Barcelona, Barcelona, Spain

Pecora V:
 Allergy Unit, Department of Pediatric Medicine, Bambino Gesù Children's Research Hospital, IRCCS, Rome, Italy

Prieto A:
 Paediatric Allergy Section, General University Hospital, Malaga, Spain

Quevedo S:
 Paediatric Allergy Section, Severo Ochoa University Hospital, Madrid, Spain

Salas A:
 Genetics, Vaccines and Infections Research Group (GENVIP), Instituto de Investigación Sanitaria de Santiago (IDIS), University of Santiago de Compostela, Santiago de Compostela, Spain

 Unidade de Xenética, Instituto de Ciencias Forenses, Facultade de Medicina, Universidade de Santiago de Compostela, and GenPoB Research Group, Instituto de Investigación Sanitaria (IDIS), Hospital Clínico Universitario de Santiago de Compostela (SERGAS), Galicia, Spain

Vazquez-Cortes S:
 Allergy Department, Clinico San Carlos Hospital, Madrid, Spain

Vila L:
 Paediatric Allergy Section, Teresa Herrera Hospital, Coruña, Spain

Martinon-Torres F:
 Paediatrics Department, Hospital Clínico Universitario de Santiago de Compostela, Coruña, Spain

 Genetics, Vaccines and Infections Research Group (GENVIP), Instituto de Investigación Sanitaria de Santiago (IDIS), University of Santiago de Compostela, Santiago de Compostela, Spain

 Centro de Investigación Biomédica en Red de Enfermedades Respiratorias (CIBERES), Instituto de Salud Carlos III, Madrid, Spain

Gomez-Carballa A:
 Genetics, Vaccines and Infections Research Group (GENVIP), Instituto de Investigación Sanitaria de Santiago (IDIS), University of Santiago de Compostela, Santiago de Compostela, Spain

 Unidade de Xenética, Instituto de Ciencias Forenses, Facultade de Medicina, Universidade de Santiago de Compostela, and GenPoB Research Group, Instituto de Investigación Sanitaria (IDIS), Hospital Clínico Universitario de Santiago de Compostela (SERGAS), Galicia, Spain

Boyle RJ:
 Section of Inflammation, Repair and Development, National Heart and Lung Institute, Imperial College London, London, United Kingdom

Vazquez-Ortiz M:
 Section of Inflammation, Repair and Development, National Heart and Lung Institute, Imperial College London, London, United Kingdom
ISSN: 22132198





Journal of Allergy and Clinical Immunology-In Practice
Editorial
ELSEVIER, RADARWEG 29, 1043 NX AMSTERDAM, NETHERLANDS, Países Bajos
Tipo de documento: Article
Volumen: 12 Número: 9
Páginas:
WOS Id: 001317926500001
ID de PubMed: 38796100
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